Left ventricular inflow obstruction due to a coronary arteriovenous fistula: a paediatric case report

BMC Cardiovascular Disorders - Tập 21 - Trang 1-6 - 2021
Ayako Chida-Nagai1, Hirokuni Yamazawa1, Takao Tsujioka1, Kota Taniguchi1, Osamu Sasaki1, Gaku Izumi1, Nobuyasu Kato2, Atsuhito Takeda1
1Department of Paediatrics, Hokkaido University Hospital, Sapporo, Japan
2Department of Cardiovascular and Thoracic Surgery, Hokkaido University Hospital, Sapporo, Japan

Tóm tắt

We report a rare case of left ventricular inflow obstruction from a branch of the left circumflex coronary artery to the right atrium caused by a coronary arteriovenous fistula (CAVF) in a young Japanese male child. The patient was diagnosed with CAVF following a heart murmur shortly after birth. The left-to-right shunt caused right ventricular volume overload and pulmonary congestion. An emergency surgical intervention was performed for the CAVF on day 6 after birth. However, by 5 years of age, his left ventricular inflow obstruction worsened. We found an abnormal blood vessel originating from the proximal part of a branch of the left circumflex coronary artery, circling the outside of the mitral valve annulus along the medial side of the coronary sinus. As the child gets older, the blood inflow into the left ventricle might get restricted further, resulting in left-sided heart failure. Our findings suggest that even after CAVF closure surgery, it is essential to monitor for complications caused by progressive dilatation of a persistent CAVF.

Tài liệu tham khảo

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BMC Cardiovascular Disorders

Tập 21

1-6

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