Progressive dystonia with marked diurnal fluctuation

Annals of Neurology - Tập 4 Số 5 - Trang 412-417 - 1978
Robert Ouvrier1
1Department of Medicine, Royal Alexandra Hospital for Children, Camperdown, NSW 2050, Australia

Tóm tắt

Abstract

Three children, 2 of them siblings, developed a progressive dystonic condition in the first decade of life. The symptoms and signs were milder in the mornings or after a daytime nap but worsened greatly later in the day. One patient became unable to walk by evening. Investigations in 2 patients revealed a reduced concentration of cerebrospinal fluid homovanillic acid. The 2 more severely affected patients showed dramatic and sustained improvement with levodopa therapy. The condition bears a clinical resemblance to some reported cases of juvenile Parkinson's disease but is probably a separate disorder.

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