Narrow trachea in mucopolysaccharidoses

Pediatric Radiology - Tập 15 - Trang 225-228 - 1985
M. E. Peters1, S. Arya1, L. O. Langer1, E. F. Gilbert1, R. Carlson1, W. Adkins2
1Dr. Mary Ellen Peters Department of Radiology, University of Wisconsin Clinical Science Center, Madison, USA
2Central Wisconsin Center for the Developmentally Disabled, Madison, USA

Tóm tắt

Nine of 56 patients with mucopolysaccharidoses (MPS) showed small tracheal diameters on their frontal chest radiographs. Autopsy of an MPS I-H (Hurler disease) patient demonstrated that the small calibre was secondary to deposition of glycosaminoglycan (mucopolysaccharide). Autopsies of two patients with other storage diseases, one with geleophysic dysplasia and one with mucolipidosis II, also exhibited compromise of their airways because of storage material accumulation.

Tài liệu tham khảo

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