Functional roles of bestrophins in ocular epithelia

Progress in Retinal and Eye Research - Tập 28 Số 3 - Trang 206-226 - 2009
Alan D. Marmorstein1,2, Harold E. Cross2, Neal S. Peachey3,4,5
1College of Optical Sciences, University of Arizona, Tucson, AZ 85711, USA
2Department of Ophthalmology and Vision Science, University of Arizona, Tucson, AZ 85711, USA
3Cole Eye Institute, Cleveland Clinic Foundation, Cleveland, OH 44195, USA
4Department of Ophthalmology, Cleveland Clinic Lerner College of Medicine of Case Western Reserve University, Cleveland, OH 44106, USA
5Research Service, Cleveland VA Medical Center, Cleveland, OH 44106, USA

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Abernethy, 1999, Calcium-antagonist drugs, N. Engl. J. Med., 341, 1447, 10.1056/NEJM199911043411907

Agbaga, 2008, Role of Stargardt-3 macular dystrophy protein (ELOVL4) in the biosynthesis of very long chain fatty acids, Proc. Natl. Acad. Sci. U.S.A., 105, 12843, 10.1073/pnas.0802607105

Al-Jumaily, 2007, Expression of three distinct families of calcium-activated chloride channel genes in the mouse dorsal root ganglion, Neurosci. Bull., 23, 293, 10.1007/s12264-007-0044-8

Allen, 1993, Intracellular calcium and myocardial function during ischemia, Adv. Exp. Med. Biol., 346, 19, 10.1007/978-1-4615-2946-0_3

Allen, 1989, The consequences of simulated ischaemia on intracellular Ca2+ and tension in isolated ferret ventricular muscle, J. Physiol., 410, 297, 10.1113/jphysiol.1989.sp017534

Allen, 2003, Role of the cardiac Na+/H+ exchanger during ischemia and reperfusion, Cardiovasc. Res., 57, 934, 10.1016/S0008-6363(02)00836-2

Allikmets, 1999, Evaluation of the Best disease gene in patients with age-related macular degeneration and other maculopathies, Hum. Genet., 104, 449, 10.1007/s004390050986

Arden, 1962, New clinical test of retinal function based upon the standing potential of the eye, Br. J. Ophthalmol., 46, 449, 10.1136/bjo.46.8.449

Arden, 1962, Changes produced by light in the standing potential of the human eye, J. Physiol., 161, 189, 10.1113/jphysiol.1962.sp006881

Arden, 1962, Some observations on the relationship between the standing potential of the human eye and the bleaching and regeneration of visual purple, J. Physiol., 161, 205, 10.1113/jphysiol.1962.sp006882

Bakall, 1999, The mutation spectrum of the bestrophin protein – functional implications, Hum. Genet., 104, 383, 10.1007/s004390050972

Bakall, 2003, Expression and localization of bestrophin during normal mouse development, Invest. Ophthalmol. Vis. Sci., 44, 3622, 10.1167/iovs.03-0030

Bakall, 2008, Bestrophin-2 is involved in the generation of intraocular pressure, Invest. Ophthalmol. Vis. Sci., 49, 1563, 10.1167/iovs.07-1338

Bakall, 2007, Enhanced accumulation of A2E in individuals homozygous or heterozygous for mutations in BEST1 (VMD2), Exp. Eye Res., 85, 34, 10.1016/j.exer.2007.02.018

Ball, S.L., Powers, P.A., Shin, H.-S., Morgans, C.W., Peachey, N.S., Gregg, R.G., 2002. Role of the β2 subunit of voltage-dependent calcium channels in the retinal outer plexiform layer. Invest. Ophthalmol. Vis. Sci. 43, 1595–1603.

Bard, 1975, Genetic counseling of families with Best macular dystrophy, Trans. Sect. Ophthalmol. Am. Acad. Ophthalmol. Otolaryngol., 79, OP865

Barro Soria, 2006, Bestrophin 1 enables Ca2+ activated Cl− conductance in epithelia, J. Biol. Chem. [Epub ahead of print]

Barro-Soria, 2008, Bestrophin 1 and 2 are components of the Ca(2+) activated Cl(−) conductance in mouse airways, Biochim. Biophys. Acta, 1783, 1993, 10.1016/j.bbamcr.2008.06.016

Ben-Shabat, 2002, Biosynthetic studies of A2E, a major fluorophore of retinal pigment epithelial lipofuscin, J. Biol. Chem., 277, 7183, 10.1074/jbc.M108981200

Best, 1905, Uber eine hereditare Maculaaffektion Beitrag zur Vererbungslehre, Z. Augenheilk, 13, 199

Birol, 2007, Oxygen distribution and consumption in the macaque retina, Am. J. Physiol. Heart Circ. Physiol., 293, H1696, 10.1152/ajpheart.00221.2007

Bishara, 1989, Evaluation of several tests in screening for chloroquine maculopathy, Eye, 3, 777, 10.1038/eye.1989.121

Blodi, 1990, Best's vitelliform dystrophy, Ophthalmic Paediatr. Genet., 11, 49

Bok, 1985, Retinal photoreceptor–pigment epithelium interactions. Friedenwald lecture, Invest. Ophthalmol. Vis. Sci., 26, 1659

Boon, 2007, Clinical and genetic heterogeneity in multifocal vitelliform dystrophy, Arch. Ophthalmol., 125, 1100, 10.1001/archopht.125.8.1100

Brake, 1996, Signaling by extracellular nucleotides, Annu. Rev. Cell Dev. Biol., 12, 519, 10.1146/annurev.cellbio.12.1.519

Brown, 2006, ISCEV standard for clinical electro-oculography (EOG) 2006, Doc. Ophthalmol., 113, 205, 10.1007/s10633-006-9030-0

Bui, 2006, Characterization of native retinal fluorophores involved in biosynthesis of A2E and lipofuscin-associated retinopathies, J. Biol. Chem., 281, 18112, 10.1074/jbc.M601380200

Burgess, 1997, Mutation of the Ca2+ channel beta subunit gene Cchb4 is associated with ataxia and seizures in the lethargic (lh) mouse, Cell, 88, 385, 10.1016/S0092-8674(00)81877-2

Burgess, 2008, ADVIRC is caused by distinct mutations in BEST1 that alter pre-mRNA splicing, J. Med. Genet. [Epub ahead of print]

Burgess, 2008, Biallelic mutation of BEST1 causes a distinct retinopathy in humans, Am. J. Hum. Genet., 82, 19, 10.1016/j.ajhg.2007.08.004

Caldwell, 1999, Bestrophin gene mutations in patients with Best vitelliform macular dystrophy, Genomics, 58, 98, 10.1006/geno.1999.5808

Caputo, 2008, TMEM16A, a membrane protein associated with calcium-dependent chloride channel activity, Science, 322, 590, 10.1126/science.1163518

Carter-Dawson, 1979, Rods and cones in the mouse retina. I. Structural analysis using light and electron microscopy, J. Comp. Neurol., 188, 245, 10.1002/cne.901880204

Chang, 2002, Retinal degeneration mutants in the mouse, Vision Res., 42, 517, 10.1016/S0042-6989(01)00146-8

Chien, 2006, Single Cl− channels activated by Ca2+ in Drosophila S2 cells are mediated by bestrophins, J. Gen. Physiol., 128, 247, 10.1085/jgp.200609581

Chung, 2004, Fundus autofluorescence and vitelliform macular dystrophy, Arch. Ophthalmol., 122, 1078, 10.1001/archopht.122.7.1078

Cross, 1974, Electro-oculography in Best's macular dystrophy, Am. J. Ophthalmol., 77, 46, 10.1016/0002-9394(74)90603-5

Dalke, 2005, Mouse mutants as models for congenital retinal disorders, Exp. Eye Res., 81, 503, 10.1016/j.exer.2005.06.004

Dawis, 1986, Dopamine influences the light peak in the perfused mammalian eye, Invest. Ophthalmol. Vis. Sci., 27, 330

Deguchi, 1994, Acidification of phagosomes and degradation of rod outer segments in rat retinal pigment epithelium, Invest. Ophthalmol. Vis. Sci., 35, 568

Duta, 2006, Regulation of basolateral Cl(−) channels in airway epithelial cells: the role of nitric oxide, J. Membr. Biol., 213, 165, 10.1007/s00232-006-0062-x

Duta, 2004, The role of bestrophin in airway epithelial ion transport, FEBS Lett., 577, 551, 10.1016/j.febslet.2004.10.068

Eldred, 1993, Age pigment structure, Nature, 364, 396, 10.1038/364396a0

Eldred, 1993, Retinal age pigments generated by self-assembling lysosomotropic detergents, Nature, 361, 724, 10.1038/361724a0

Elliott, 1992, Metabolic changes during ischaemia and their role in contractile failure in isolated ferret hearts, J. Physiol., 454, 467, 10.1113/jphysiol.1992.sp019274

Esumi, 2004, Analysis of the VMD2 promoter and implication of E-box binding factors in its regulation, J. Biol. Chem., 279, 19064, 10.1074/jbc.M309881200

Feeney-Burns, 1983, The fate of the phagosome: conversion to ‘age pigment’ and impact in human retinal pigment epithelium, Trans. Ophthalmol. Soc. U. K., 103, 416

Felbor, 1997, Adult vitelliform macular dystrophy is frequently associated with mutations in the peripherin/RDS gene, Hum. Mutat., 10, 301, 10.1002/(SICI)1098-1004(1997)10:4<301::AID-HUMU6>3.0.CO;2-J

Finnemann, 1997, Phagocytosis of rod outer segments by retinal pigment epithelial cells requires alpha(v)beta5 integrin for binding but not for internalization, Proc. Natl. Acad. Sci. U.S.A., 94, 12932, 10.1073/pnas.94.24.12932

Finnemann, 1999, Macrophage and retinal pigment epithelium phagocytosis: apoptotic cells and photoreceptors compete for alphavbeta3 and alphavbeta5 integrins, and protein kinase C regulates alphavbeta5 binding and cytoskeletal linkage, J. Exp. Med., 190, 861, 10.1084/jem.190.6.861

Fishman, 1993, Visual acuity in patients with best vitelliform macular dystrophy, Ophthalmology, 100, 1665, 10.1016/S0161-6420(93)31420-X

Foulds, 1966, The effects of detachment of the retina on induced and resting ocular potentials in the rabbit, Invest. Ophthalmol. Vis. Sci., 5, 93

Frangieh, 1982, A histopathologic study of Best's macular dystrophy, Arch. Ophthalmol., 100, 1115, 10.1001/archopht.1982.01030040093017

Fries, 2004, Expression of P2Y1, P2Y2, P2Y4, and P2Y6 receptor subtypes in the rat retina, Invest. Ophthalmol. Vis. Sci., 45, 3410, 10.1167/iovs.04-0141

Fujii, 1992, Direct evidence for a basolateral membrane Cl− conductance in toad retinal pigment epithelium, Am. J. Physiol., 262, C374, 10.1152/ajpcell.1992.262.2.C374

Gallemore, 1998, Light induced responses of the retinal pigment epithelium, 175

Gallemore, 1989, Effects of DIDS on the chick retinal pigment epithelium. II. Mechanism of the light peak and other responses originating at the basal membrane, J. Neurosci., 9, 1977, 10.1523/JNEUROSCI.09-06-01977.1989

Gallemore, 1990, Effects of dopamine on the chick retinal pigment epithelium. Membrane potentials and light-evoked responses, Invest. Ophthalmol. Vis. Sci., 31, 67

Gallemore, 1993, Light-evoked modulation of basolateral membrane Cl− conductance in chick retinal pigment epithelium: the light peak and fast oscillation, J. Neurophysiol., 70, 1669, 10.1152/jn.1993.70.4.1669

Goldberg, 1989, Histopathologic study of autosomal dominant vitreoretinochoroidopathy. Peripheral annular pigmentary dystrophy of the retina, Ophthalmology, 96, 1736, 10.1016/S0161-6420(89)32663-7

Gomez, 2001, The gene causing the Best's macular dystrophy (BMD) encodes a putative ion exchanger, DNA Seq., 12, 431, 10.3109/10425170109084470

Gouras, 1963, The EOG in chloroquine and other retinopathies, Arch. Ophthalmol., 70, 629, 10.1001/archopht.1963.00960050631009

Guziewicz, 2007, Bestrophin gene mutations cause canine multifocal retinopathy: a novel animal model for best disease, Invest. Ophthalmol. Vis. Sci., 48, 1959, 10.1167/iovs.06-1374

Hagen, 2005, The bestrophin family of anion channels: identification of prokaryotic homologues, Mol. Membr. Biol., 22, 291, 10.1080/09687860500129711

Hall, 1991, ROS ingestion by RPE cells is turned off by increased protein kinase C activity and by increased calcium, Exp. Eye Res., 52, 591, 10.1016/0014-4835(91)90061-I

Han, 1995, Histopathologic study of autosomal dominant vitreoretinochoroidopathy in a 26-year-old woman, Arch. Ophthalmol., 113, 1561, 10.1001/archopht.1995.01100120093017

Hartzell, 2005, Looking chloride channels straight in the eye: bestrophins, lipofuscinosis, and retinal degeneration, Physiology (Bethesda), 20, 292, 10.1152/physiol.00021.2005

Hartzell, 2008, Molecular physiology of bestrophins: multifunctional membrane proteins linked to best disease and other retinopathies, Physiol. Rev., 88, 639, 10.1152/physrev.00022.2007

Hartzell, 2008, Anoctamin/TMEM16 family members are Ca2+-activated Cl− channels, J. Physiol

Haugh, 1990, Mathematical models of the spatial distribution of retinal oxygen tension and consumption, including changes upon illumination, Ann. Biomed. Eng., 18, 19, 10.1007/BF02368415

Hu, 2001, A cell culture medium that supports the differentiation of human retinal pigment epithelium into functionally polarized monolayers, Mol. Vis., 7, 14

Jarc-Vidmar, 2003, Fundus autofluorescence imaging in Best's vitelliform dystrophy, Klin. Monatsbl. Augenheilkd., 220, 861, 10.1055/s-2003-812555

Joseph, 1992, Alpha-1-adrenergic modulation of K and Cl transport in bovine retinal pigment epithelium, J. Gen. Physiol., 99, 263, 10.1085/jgp.99.2.263

Kaemmerer, 2007, Effects of lipid peroxidation-related protein modifications on RPE lysosomal functions and POS phagocytosis, Invest. Ophthalmol. Vis. Sci., 48, 1342, 10.1167/iovs.06-0549

Karan, 2005, Lipofuscin accumulation, abnormal electrophysiology, and photoreceptor degeneration in mutant ELOVL4 transgenic mice: a model for macular degeneration, Proc. Natl. Acad. Sci. U.S.A., 102, 4164, 10.1073/pnas.0407698102

Karl, 2008, Endogenous Gas6 and Ca2+-channel activation modulate phagocytosis by retinal pigment epithelium, Cell Signal., 20, 1159, 10.1016/j.cellsig.2008.02.005

Karmazyn, 2001, The myocardial Na+/H+ exchanger: a potential therapeutic target for the prevention of myocardial ischaemic and reperfusion injury and attenuation of postinfarction heart failure, Drugs, 61, 375, 10.2165/00003495-200161030-00006

Kaufman, 1982, Autosomal dominant vitreoretinochoroidopathy, Arch. Ophthalmol., 100, 272, 10.1001/archopht.1982.01030030274008

Keeler, 1924, The inheritance of a retinal abnormality in white mice, Proc. Natl. Acad. Sci. U.S.A., 10, 329, 10.1073/pnas.10.7.329

Khosravani, 2006, Voltage-gated calcium channels and idiopathic generalized epilepsies, Physiol. Rev., 86, 941, 10.1152/physrev.00002.2006

Kikawada, 1968, Variations in the corneo-retinal standing potential of the vertebrate eye during light and dark adaptations, Jpn. J. Physiol., 18, 687, 10.2170/jjphysiol.18.687

Kim, 2007, The all-trans-retinal dimer series of lipofuscin pigments in retinal pigment epithelial cells in a recessive Stargardt disease model, Proc. Natl. Acad. Sci. U.S.A., 104, 19273, 10.1073/pnas.0708714104

Kim, 2006, Photooxidation of A2-PE, a photoreceptor outer segment fluorophore, and protection by lutein and zeaxanthin, Exp. Eye Res., 82, 828, 10.1016/j.exer.2005.10.004

Kramer, 2003, Ten novel mutations in VMD2 associated with Best macular dystrophy (BMD), Hum. Mutat., 22, 418, 10.1002/humu.9189

Kramer, 2004, Cloning and characterization of the murine Vmd2 RFP-TM gene family, Cytogenet. Genome Res., 105, 107, 10.1159/000078016

Kramer, 2000, Mutations in the VMD2 gene are associated with juvenile-onset vitelliform macular dystrophy (Best disease) and adult vitelliform macular dystrophy but not age-related macular degeneration, Eur. J. Hum. Genet., 8, 286, 10.1038/sj.ejhg.5200447

Lafaut, 2001, Clinical and electrophysiological findings in autosomal dominant vitreoretinochoroidopathy: report of a new pedigree, Graefes Arch. Clin. Exp. Ophthalmol., 239, 575, 10.1007/s004170100318

Lang, 2003, Intracellular pH activates membrane-bound Na(+)/H(+) exchanger and vacuolar H(+)-ATPase in human embryonic kidney (HEK) cells, Cell Physiol. Biochem., 13, 257, 10.1159/000074540

LaVail, 1983, Outer segment disc shedding and phagocytosis in the outer retina, Trans. Ophthalmol. Soc. U. K., 103, 397

Lee, 1992, Changes in intracellular free calcium concentration during long exposures to simulated ischemia in isolated mammalian ventricular muscle, Circ. Res., 71, 58, 10.1161/01.RES.71.1.58

Liu, 2000, The biosynthesis of A2E, a fluorophore of aging retina, involves the formation of the precursor, A2-PE, in the photoreceptor outer segment membrane, J. Biol. Chem., 275, 29354, 10.1074/jbc.M910191199

Liu, 2008, Restoration of lysosomal pH in RPE cells from cultured human and ABCA4(−/−) mice: pharmacologic approaches and functional recovery, Invest. Ophthalmol. Vis. Sci., 49, 772, 10.1167/iovs.07-0675

Luo, 2005, Decreased neuronal death in Na+/H+ exchanger isoform 1-null mice after in vitro and in vivo ischemia, J. Neurosci., 25, 11256, 10.1523/JNEUROSCI.3271-05.2005

Maminishkis, 2006, Confluent monolayers of cultured human fetal retinal pigment epithelium exhibit morphology and physiology of native tissue, Invest. Ophthalmol. Vis. Sci., 47, 3612, 10.1167/iovs.05-1622

Marmor, 1979, “Vitelliform” lesions in adults, Ann. Ophthalmol., 11, 1705

Marmor, 1990, Control of subretinal fluid: experimental and clinical studies, Eye, 4, 340, 10.1038/eye.1990.46

Marmor, 1994, Conditions necessary for the formation of serous detachment. Experimental evidence from the cat, Arch. Ophthalmol., 112, 830, 10.1001/archopht.1994.01090180130047

Marmorstein, 1998, Morphogenesis of the retinal pigment epithelium: toward understanding retinal degenerative diseases, Ann. N. Y. Acad. Sci., 857, 1, 10.1111/j.1749-6632.1998.tb10102.x

Marmorstein, 2007, Focus on molecules: bestrophin (best-1), Exp. Eye Res., 85, 423, 10.1016/j.exer.2006.03.021

Marmorstein, 2007, The challenge of modeling macular degeneration in mice, Trends Genet., 23, 225, 10.1016/j.tig.2007.03.001

Marmorstein, 2000, Bestrophin, the product of the Best vitelliform macular dystrophy gene (VMD2), localizes to the basolateral plasma membrane of the retinal pigment epithelium, Proc. Natl. Acad. Sci. U.S.A., 97, 12758, 10.1073/pnas.220402097

Marmorstein, 2003, In vivo gene transfer as a means to study the physiology and morphogenesis of the retinal pigment epithelium in the rat, Methods, 30, 277, 10.1016/S1046-2023(03)00034-3

Marmorstein, 2004, A model of best vitelliform macular dystrophy in rats, Invest. Ophthalmol. Vis. Sci., 45, 3733, 10.1167/iovs.04-0307

Marmorstein, 2002, Bestrophin interacts physically and functionally with protein phosphatase 2A, J. Biol. Chem., 277, 30591, 10.1074/jbc.M204269200

Marmorstein, 2006, The light peak of the electroretinogram is dependent on voltage-gated calcium channels and antagonized by bestrophin (best-1), J. Gen. Physiol., 127, 577, 10.1085/jgp.200509473

Marquardt, 1998, Mutations in a novel gene, VMD2, encoding a protein of unknown properties cause juvenile-onset vitelliform macular dystrophy (Best's disease), Hum. Mol. Genet., 7, 1517, 10.1093/hmg/7.9.1517

Masuoka, 2005, Beneficial effect of FR183998, a Na+/H+ exchanger inhibitor, on porcine pancreas allotransplantation retrieved from non-heart-beating donors, Transplant Proc., 37, 223, 10.1016/j.transproceed.2004.12.227

Mentzer, 2008, Sodium–hydrogen exchange inhibition by cariporide to reduce the risk of ischemic cardiac events in patients undergoing coronary artery bypass grafting: results of the EXPEDITION study, Ann. Thorac. Surg., 85, 1261, 10.1016/j.athoracsur.2007.10.054

Milenkovic, 2008, Molecular evolution and functional divergence of the bestrophin protein family, BMC Evol. Biol., 8, 72, 10.1186/1471-2148-8-72

Milenkovic, 2007, Insertion and topology of normal and mutant bestrophin-1 in the endoplasmic reticulum membrane, J. Biol. Chem., 282, 1313, 10.1074/jbc.M607383200

Mohler, 1981, Long-term evaluation of patients with Best's vitelliform dystrophy, Ophthalmology, 88, 688, 10.1016/S0161-6420(81)34965-3

Mullins, 2007, Differential macular and peripheral expression of bestrophin in human eyes and its implication for best disease, Invest. Ophthalmol. Vis. Sci., 48, 3372, 10.1167/iovs.06-0868

Mullins, 2005, Late development of vitelliform lesions and flecks in a patient with best disease: clinicopathologic correlation, Arch. Ophthalmol., 123, 1588, 10.1001/archopht.123.11.1588

Nao-i, 1989, Effects of melatonin on the chick retinal pigment epithelium: membrane potentials and light-evoked responses, Exp. Eye Res., 49, 573, 10.1016/S0014-4835(89)80056-9

Negi, 1983, The resorption of subretinal fluid after diffuse damage to the retinal pigment epithelium, Invest. Ophthalmol. Vis. Sci., 24, 1475

Nordstrom, 1980, Dominantly inherited macular degeneration (Best's disease) in a homozygous father with 11 children, Clin. Genet., 18, 211, 10.1111/j.1399-0004.1980.tb00874.x

O'Driscoll, 2008, Expression, localization, and functional properties of Bestrophin 3 channel isolated from mouse heart, Am. J. Physiol. Cell Physiol., 295, C1610, 10.1152/ajpcell.00461.2008

O'Gorman, 1988, Histopathologic findings in Best's vitelliform macular dystrophy, Arch. Ophthalmol., 106, 1261, 10.1001/archopht.1988.01060140421045

Pacione, 2003, Progress toward understanding the genetic and biochemical mechanisms of inherited photoreceptor degenerations, Annu. Rev. Neurosci., 26, 657, 10.1146/annurev.neuro.26.041002.131416

Park, 1999, Changes in intracellular Na+ and pH in rat heart during ischemia: role of Na+/H+ exchanger, Am. J. Physiol., 276, H1581

Peachey, 2002, Noninvasive recording and response characteristics of the rat dc-electroretinogram, Vis. Neurosci., 19, 693, 10.1017/S0952523802196015

Peters, 2006, Inhibition of lysosomal degradation in retinal pigment epithelium cells induces exocytosis of phagocytic residual material at the basolateral plasma membrane, Ophthalmic Res., 38, 83, 10.1159/000090268

Peterson, 1997, Extracellular ATP activates calcium signaling, ion, and fluid transport in retinal pigment epithelium, J. Neurosci., 17, 2324, 10.1523/JNEUROSCI.17-07-02324.1997

Petrukhin, 1998, Identification of the gene responsible for Best macular dystrophy, Nat. Genet., 19, 241, 10.1038/915

Pianta, 2003, In vivo micropathology of Best macular dystrophy with optical coherence tomography, Exp. Eye Res., 76, 203, 10.1016/S0014-4835(02)00280-4

Pifferi, 2006, Bestrophin-2 is a candidate calcium-activated chloride channel involved in olfactory transduction, Proc. Natl. Acad. Sci. U.S.A., 103, 12929, 10.1073/pnas.0604505103

Piper, 1996, The role of Na+/H+ exchange in ischemia-reperfusion, Basic Res. Cardiol., 91, 191, 10.1007/BF00788905

Piper, 2003, Cellular mechanisms of ischemia-reperfusion injury, Ann. Thorac. Surg., 75, S644, 10.1016/S0003-4975(02)04686-6

Qu, 2006, The anion-selective pore of the bestrophins, a family of chloride channels associated with retinal degeneration, J. Neurosci., 26, 5411, 10.1523/JNEUROSCI.5500-05.2006

Qu, 2004, Mouse bestrophin-2 is a bona fide Cl(−) channel: identification of a residue important in anion binding and conduction, J. Gen. Physiol., 123, 327, 10.1085/jgp.200409031

Qu, 2004, Determinants of anion permeation in the second transmembrane domain of the mouse bestrophin-2 chloride channel, J. Gen. Physiol., 124, 371, 10.1085/jgp.200409108

Qu, 2008, Bestrophin Cl− channels are highly permeable to HCO3, Am. J. Physiol. Cell Physiol., 294, C1371, 10.1152/ajpcell.00398.2007

Qu, 2003, Two bestrophins cloned from Xenopus laevis oocytes express Ca(2+)-activated Cl(−) currents, J. Biol. Chem., 278, 49563, 10.1074/jbc.M308414200

Quinn, 2001, Adrenergic receptor activated ion transport in human fetal retinal pigment epithelium, Invest. Ophthalmol. Vis. Sci., 42, 255

Radu, 2004, Light exposure stimulates formation of A2E oxiranes in a mouse model of Stargardt's macular degeneration, Proc. Natl. Acad. Sci. U.S.A., 101, 5928, 10.1073/pnas.0308302101

Radu, 2008, Accelerated accumulation of lipofuscin pigments in the RPE of a mouse model for ABCA4-mediated retinal dystrophies following Vitamin A supplementation, Invest. Ophthalmol. Vis. Sci., 49, 3821, 10.1167/iovs.07-1470

Rakoczy, 1996, Correlation between autofluorescent debris accumulation and the presence of partially processed forms of cathepsin D in cultured retinal pigment epithelial cells challenged with rod outer segments, Exp. Eye Res., 63, 159, 10.1006/exer.1996.0104

Renner, 2005, Late onset is common in best macular dystrophy associated with VMD2 gene mutations, Ophthalmology, 112, 586, 10.1016/j.ophtha.2004.10.041

Rock, 2008, The transmembrane protein TMEM16A is required for normal development of the murine trachea, Dev. Biol., 321, 141, 10.1016/j.ydbio.2008.06.009

Roider, 1997, Autosomal dominant vitreoretinochoroidopathy, Retina, 17, 294, 10.1097/00006982-199707000-00003

Rosenthal, 2006, Expression of bestrophin-1, the product of the VMD2 gene, modulates voltage-dependent Ca2+ channels in retinal pigment epithelial cells, FASEB J., 20, 178, 10.1096/fj.05-4495fje

Schroeder, 2008, Expression cloning of TMEM16A as a calcium-activated chloride channel subunit, Cell, 134, 1019, 10.1016/j.cell.2008.09.003

Sodi, 2007, A novel mutation in the VMD2 gene in an Italian family with Best maculopathy, J. Fr. Ophtalmol., 30, 616, 10.1016/S0181-5512(07)89667-7

Spaide, 2006, Vitelliform macular dystrophy, Ophthalmology, 113, 1392, 10.1016/j.ophtha.2006.03.023

Sparrow, 2005, RPE lipofuscin and its role in retinal pathobiology, Exp. Eye Res., 80, 595, 10.1016/j.exer.2005.01.007

Sparrow, 2008, A2E, a pigment of RPE lipofuscin, is generated from the precursor, A2PE by a lysosomal enzyme activity, Adv. Exp. Med. Biol., 613, 393, 10.1007/978-0-387-74904-4_46

Srivastava, 2008, A variant of the Ca2+-activated Cl channel Best3 is expressed in mouse exocrine glands, J. Membr. Biol., 222, 43, 10.1007/s00232-008-9098-4

Stanton, 2006, Hydrodynamic properties of porcine bestrophin-1 in Triton X-100, Biochim. Biophys. Acta, 1758, 241, 10.1016/j.bbamem.2006.01.024

Stanton, 2008, A comparison of the phenotypes of bestrophin knock-in and knock-out mice: implications for the pathogenesis of best vitelliform macular degeneration, Invest. Ophthalmol. Vis. Sci., 49, 5188

Steinberg, 1985, Interactions between the retinal pigment epithelium and the neural retina, Doc. Ophthalmol., 60, 327, 10.1007/BF00158922

Steinberg, 1983, Three light-evoked responses of the retinal pigment epithelium, Vision Res., 23, 1315, 10.1016/0042-6989(83)90107-4

Stohr, 2002, Three novel human VMD2-like genes are members of the evolutionary highly conserved RFP-TM family, Eur. J. Hum. Genet., 10, 281, 10.1038/sj.ejhg.5200796

Strauss, 2008, Direct Interaction of bestrophin-1 and beta-subunits of voltage-dependent calcium channels, Invest. Ophthalmol. Vis. Sci., 49, 5182

Sun, 2002, The vitelliform macular dystrophy protein defines a new family of chloride channels, Proc. Natl. Acad. Sci. U.S.A., 99, 4008, 10.1073/pnas.052692999

Szel, 1996, Distribution of cone photoreceptors in the mammalian retina, Microsc. Res. Tech., 35, 445, 10.1002/(SICI)1097-0029(19961215)35:6<445::AID-JEMT4>3.0.CO;2-H

ten Hove, 2007, Combined blockade of the Na+ channel and the Na+/H+ exchanger virtually prevents ischemic Na+ overload in rat hearts, Mol. Cell. Biochem., 297, 101, 10.1007/s11010-006-9334-0

Thorburn, 1978, EOG in a large family with hereditary macular degeneration. (Best's vitelliform macular dystrophy) identification of gene carriers, Acta Ophthalmol. (Copenh.), 56, 455, 10.1111/j.1755-3768.1978.tb05699.x

Tsunenari, 2003, Structure–function analysis of the bestrophin family of anion channels, J. Biol. Chem., 278, 41114, 10.1074/jbc.M306150200

Vasireddy, 2006, Elovl4 5-bp-deletion knock-in mice develop progressive photoreceptor degeneration, Invest. Ophthalmol. Vis. Sci., 47, 4558, 10.1167/iovs.06-0353

Vasireddy, 2007, Loss of functional ELOVL4 depletes very long-chain fatty acids (> or =C28) and the unique omega-O-acylceramides in skin leading to neonatal death, Hum. Mol. Genet., 16, 471, 10.1093/hmg/ddl480

von Ruckmann, 1997, In vivo fundus autofluorescence in macular dystrophies, Arch. Ophthalmol., 115, 609, 10.1001/archopht.1997.01100150611006

Wabbels, 2006, Genotype–phenotype correlation and longitudinal course in ten families with Best vitelliform macular dystrophy, Graefes Arch. Clin. Exp. Ophthalmol., 244, 1453, 10.1007/s00417-006-0286-6

Wang, 2003, Mice with a null mutation in the NHE1 Na+/H+ exchanger are resistant to cardiac ischemia-reperfusion injury, Circ. Res., 93, 776, 10.1161/01.RES.0000094746.24774.DC

Wangsa-Wirawan, 2003, Retinal oxygen: fundamental and clinical aspects, Arch. Ophthalmol., 121, 547, 10.1001/archopht.121.4.547

Weingeist, 1982, Histopathology of Best's macular dystrophy, Arch. Ophthalmol., 100, 1108, 10.1001/archopht.1982.01030040086016

Weng, 1999, Insights into the function of Rim protein in photoreceptors and etiology of Stargardt's disease from the phenotype in abcr knockout mice, Cell, 98, 13, 10.1016/S0092-8674(00)80602-9

White, 2000, VMD2 mutations in vitelliform macular dystrophy (Best disease) and other maculopathies, Hum. Mutat., 15, 301, 10.1002/(SICI)1098-1004(200004)15:4<301::AID-HUMU1>3.0.CO;2-N

Won, 2008, Membrane frizzled-related protein is necessary for the normal development and maintenance of photoreceptor outer segments, Vis. Neurosci., 25, 563, 10.1017/S0952523808080887

Wu, 2006, Functional abnormalities in the retinal pigment epithelium of CFTR mutant mice, Exp. Eye Res., 83, 424, 10.1016/j.exer.2006.01.021

Wu, 2007, Voltage-dependent calcium channel CaV1.3 subunits regulate the light peak of the electroretinogram, J. Neurophysiol., 97, 3731, 10.1152/jn.00146.2007

Wu, 2004, Light-evoked responses of the mouse retinal pigment epithelium, J. Neurophysiol., 91, 1134, 10.1152/jn.00958.2003

Xiao, 2008, Regulation of bestrophin Cl channels by calcium: role of the C terminus, J. Gen. Physiol., 132, 681, 10.1085/jgp.200810056

Xiao, 1999, Role of Na(+)/H(+) exchanger during ischemia and preconditioning in the isolated rat heart, Circ. Res., 85, 723, 10.1161/01.RES.85.8.723

Xiao, 2000, Activity of the Na(+)/H(+) exchanger is critical to reperfusion damage and preconditioning in the isolated rat heart, Cardiovasc. Res., 48, 244, 10.1016/S0008-6363(00)00166-8

Yang, 2008, TMEM16A confers receptor-activated calcium-dependent chloride conductance, Nature, 455, 1210, 10.1038/nature07313

Yao, 2003, The role of HCO3(−)-dependent mechanisms in pHi regulation during O2 deprivation, Neuroscience, 117, 29, 10.1016/S0306-4522(02)00821-7

Yao, 2004, Calcium and pH homeostasis in neurons during hypoxia and ischemia, Cell Calcium, 36, 247, 10.1016/j.ceca.2004.02.013

Yardley, 2004, Mutations of VMD2 splicing regulators cause nanophthalmos and autosomal dominant vitreoretinochoroidopathy (ADVIRC), Invest. Ophthalmol. Vis. Sci., 45, 3683, 10.1167/iovs.04-0550

Yu, 2006, The bestrophin mutation A243V, linked to adult-onset vitelliform macular dystrophy, impairs its chloride channel function, Invest. Ophthalmol. Vis. Sci., 47, 4956, 10.1167/iovs.06-0524

Yu, 2008, The best disease-linked Cl− channel hBest1 regulates Ca V 1 (L-type) Ca2+ channels via src-homology-binding domains, J. Neurosci., 28, 5660, 10.1523/JNEUROSCI.0065-08.2008

Zhang, 2009, Enhanced inflow and outflow rates despite lower IOP in Bestrophin-2 deficient mice, Invest. Ophthalmol. Vis. Sci., 50, 765, 10.1167/iovs.08-2501

Zhou, 2007, Experimental selection for Drosophila survival in extremely low O2 environment, PLoS ONE, 2, e490, 10.1371/journal.pone.0000490

Zhou, 2004, Na+/H+ exchanger 1 deficiency alters gene expression in mouse brain, Physiol. Genomics, 18, 331, 10.1152/physiolgenomics.00076.2004

Zhuk, 2006, Peripherin/RDS and VMD2 mutations in macular dystrophies with adult-onset vitelliform lesion, Mol. Vis., 12, 811