Sample size calculations for comparative studies of medical tests for detecting presence of disease

Statistics in Medicine - Tập 21 Số 6 - Trang 835-852 - 2002
Todd A. Alonzo1, Margaret S. Pepe2, Chaya S. Moskowitz2
1Department of Preventive Medicine, University of Southern California, Los Angeles, CA 90089, U.S.A.
2Department of Biostatistics, University of Washington, Seattle, WA 98195, U.S.A.

Tóm tắt

Abstract

Technologic advances give rise to new tests for detecting disease in many fields, including cancer and sexually transmitted disease. Before a new disease screening test is approved for public use, its accuracy should be shown to be better than or at least not inferior to an existing test. Standards do not yet exist for designing and analysing studies to address this issue. Established principles for the design of therapeutic studies can be adapted for studies of screening tests. In particular, drawing upon methods for superiority and non‐inferiority studies of therapeutic agents, we propose that confidence intervals for the relative accuracy of dichotomous tests drive the design of comparative studies of disease screening tests. We derive sample size formulae for a variety of designs, including studies where patients undergo several tests and studies where patients receive only one of the tests under evaluation. Both cohort and case‐control study designs are considered. Modifications to the confidence intervals and sample size formulae are discussed to accommodate studies where, because of the invasive nature of definitive testing, true disease status can only be obtained for subjects who are positive on one or more of the screening tests. The methods proposed are applied to a study comparing a modified pap test to the conventional pap for cervical cancer screening. The impact of error in the gold standard reference test on the design and evaluation of comparative screening test studies is also discussed. Copyright © 2002 John Wiley & Sons, Ltd.

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Tài liệu tham khảo

ICH E9 Expert Working Group, 1999, Statistical principles for clinical trials: ICH harmonised tripartite guideline, Statistics in Medicine, 18, 1905

Schatzkin A, 1987, Comparing new and old screening tests when a reference procedure cannot be performed on all screens, American Journal of Epidemiology, 25, 672, 10.1093/oxfordjournals.aje.a114580

10.1097/00001648-199701000-00017

10.1093/biostatistics/2.3.249

10.1002/sim.4780141611

10.1002/(SICI)1097-0258(19981015)17:19<2219::AID-SIM919>3.0.CO;2-1

10.1001/jama.282.11.1061

10.1016/S0960-9776(98)90062-5

10.7326/0003-4819-120-8-199404150-00008

10.1259/0007-1285-60-719-1071

10.1148/radiology.167.2.3357976

Hanley JA, 1989, Receiver operating characteristic (ROC) methodology: the state of the art, Critical Reviews in Diagnostic Imaging, 29, 307

10.1148/radiology.175.2.2183290

10.1056/NEJM197810262991705

10.1002/sim.4780060402

10.1002/sim.4780101205

Reid MC, 1995, Use of methodological standards in diagnostic test research. Getting better but still not good, Journal of the American Medical Association, 274, 645, 10.1001/jama.1995.03530080061042

10.1177/096228029900800203

Johnson RA, 1992, Applied Multivariate Statistical Analysis

10.1002/sim.4780111110

McCroryDC MatcharDB BastianL DattaS HasselbladV MickeyJ MyersE NandaK.Evaluation of cervical cytology. Evidence Report/Technology Assessment No. 5 AHCPR Publication No. 99‐E0101 Rockville Maryland 1999.

Cole P, 1980, Basic issues in population screening for cancer, Journal of National Cancer Institute, 5, 1263

10.1016/0895-4356(91)90128-V

10.1111/j.1471-0528.1998.tb10175.x

10.1002/(SICI)1097-0142(19981115)83:10<2150::AID-CNCR13>3.0.CO;2-0

10.1001/jama.283.1.81

10.2307/2530161

10.2307/2530967

Walter SD, 1988, Estimation of test error rates, disease prevalence and relative risk from misclassified data: a review, Journal of Clinical Epidemiology, 41, 923, 10.1016/0895-4356(88)90110-2

10.1021/bi00268a044

10.2307/2530705

10.1002/sim.4780060107

10.2307/2531961

10.2307/2532131

10.1002/sim.4780110909

10.1002/(SICI)1097-0258(19981015)17:19<2207::AID-SIM920>3.0.CO;2-Y

10.1002/(SICI)1097-0258(19970615)16:11<1263::AID-SIM550>3.0.CO;2-M

10.1016/S0022-5347(01)64147-8